Publication:
Clinical exome sequencing in neuromuscular diseases: an experience from Turkey

dc.contributor.departmentN/A
dc.contributor.departmentN/A
dc.contributor.departmentN/A
dc.contributor.departmentN/A
dc.contributor.departmentN/A
dc.contributor.departmentN/A
dc.contributor.departmentN/A
dc.contributor.kuauthorBörklü Yücel, Esra
dc.contributor.kuauthorDemiriz, Çiğdem
dc.contributor.kuauthorAvcı, Şahin
dc.contributor.kuauthorVanlı-Yavuz, Ebru Nur
dc.contributor.kuauthorEraslan, Serpil
dc.contributor.kuauthorOflazer, Piraye
dc.contributor.kuauthorKayserili, Hülya
dc.contributor.kuprofileOther
dc.contributor.kuprofileN/A
dc.contributor.kuprofileFaculty Member
dc.contributor.kuprofileDoctor
dc.contributor.kuprofileResearcher
dc.contributor.kuprofileFaculty Member
dc.contributor.kuprofileFaculty Member
dc.contributor.researchcenterKoç University Research Center for Translational Medicine (KUTTAM) / Koç Üniversitesi Translasyonel Tıp Araştırma Merkezi (KUTTAM)
dc.contributor.schoolcollegeinstituteSchool of Medicine
dc.contributor.schoolcollegeinstituteN/A
dc.contributor.schoolcollegeinstituteSchool of Medicine
dc.contributor.schoolcollegeinstituteSchool of Medicine
dc.contributor.schoolcollegeinstituteSchool of Medicine
dc.contributor.schoolcollegeinstituteSchool of Medicine
dc.contributor.schoolcollegeinstituteSchool of Medicine
dc.contributor.unitKoç University Hospital
dc.contributor.yokidN/A: N/A
dc.contributor.yokidN/A
dc.contributor.yokid251177
dc.contributor.yokidN/A
dc.contributor.yokidN/A
dc.contributor.yokid7945
dc.date.accessioned2024-11-09T23:10:45Z
dc.date.issued2020
dc.description.abstractNeuromuscular diseases (NMDs) encompass a variety of ailments from muscular dystrophies to ataxias, in the course of which the functioning of the muscles is eventually either directly or indirectly impaired. The clinical diagnosis of a particular NMD is not always straightforward due to the clinical and genetic heterogeneity of the disorders under investigation. Traditional diagnostic tools such as electrophysiological tests and muscle biopsies are both invasive and painful methods, causing the patients to be reluctant. Next-generation sequencing, on the other hand, emerged as an alternative method for the diagnosis of NMDs, both with its minimally invasive nature and fast processing period. In this study, clinical exome sequencing (CES) was applied to a cohort of 70 probands in Turkey, 44 of whom received a final diagnosis, representing a diagnostic rate of 62.9%. Out of the 50 mutations identified to be causal, 26 were novel in the known 27 NMD genes. Two probands had complex/blended phenotypes. Molecular confirmation of clinical diagnosis of NMDs has a major prognostic impact and is crucial for the management and the possibility of alternative reproductive options. CES, which has been increasingly adopted to diagnose single-gene disorders, is also a powerful tool for revealing the etiopathogenesis in complex/blended phenotypes, as observed in two probands of the cohort.
dc.description.indexedbyWoS
dc.description.indexedbyScopus
dc.description.indexedbyPubMed
dc.description.issue8
dc.description.openaccessNO
dc.description.publisherscopeInternational
dc.description.volume41
dc.identifier.doi10.1007/s10072-020-04304-w
dc.identifier.eissn1590-3478
dc.identifier.issn1590-1874
dc.identifier.scopus2-s2.0-85081027177
dc.identifier.urihttp://dx.doi.org/10.1007/s10072-020-04304-w
dc.identifier.urihttps://hdl.handle.net/20.500.14288/9532
dc.identifier.wos551151100027
dc.keywordsNext-generation sequencing (NGS)
dc.keywordsClinical exome sequencing (CES)
dc.keywordsNeuromuscular disease (NMD)
dc.keywordsDual diagnosis
dc.keywordsDysferlinopathy
dc.keywordsSarcoglycanopathy
dc.languageEnglish
dc.publisherSpringer-Verlag Italia Srl
dc.sourceNeurological Sciences
dc.subjectClinical neurology
dc.subjectNeurosciences
dc.titleClinical exome sequencing in neuromuscular diseases: an experience from Turkey
dc.typeJournal Article
dspace.entity.typePublication
local.contributor.authorid0000-0002-1326-0608
local.contributor.authoridN/A
local.contributor.authorid0000-0001-9545-6657
local.contributor.authorid0000-0001-6915-7493
local.contributor.authorid0000-0002-7674-7384
local.contributor.authorid0000-0001-8202-5313
local.contributor.authorid0000-0003-0376-499X
local.contributor.kuauthorBörklü Yücel, Esra
local.contributor.kuauthorDemiriz, Çiğdem
local.contributor.kuauthorAvcı, Şahin
local.contributor.kuauthorVanlı-Yavuz, Ebru Nur
local.contributor.kuauthorEraslan, Serpil
local.contributor.kuauthorOflazer, Piraye
local.contributor.kuauthorKayserili, Hülya

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